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SNCA – Parkinson Disease

Alpha-synuclein, encoded by SNCA, is a presynaptic protein central to the pathogenesis of Parkinson disease (PD) through its propensity to aggregate into Lewy bodies and neurites. Familial and sporadic PD cases with missense mutations and gene multiplications of SNCA have underscored its causal role in autosomal dominant PD.

Clinical Validity

SNCA–PD is classified as Definitive based on numerous unrelated families demonstrating autosomal dominant inheritance, presence of both point mutations and copy number variants, segregation in multiple pedigrees, and concordant functional studies. Segregation has been observed across more than 15 affected relatives in distinct kindreds, with confirmation of pathognomonic Lewy pathology and clinical phenotypes consistent with PD (gene_disease_association: Definitive; rationale: "Multiple unrelated kindreds, autosomal dominant segregation, missense variants and multiplications, concordant pathology and function").

Genetic Evidence

The inheritance mode is Autosomal dominant. Key pathogenic variants include missense mutations such as c.157G>A (p.Ala53Thr) and c.136G>A (p.Glu46Lys), and SNCA duplications/triplications associated with early onset and rapidly progressive PD (15144854). Segregation analyses in families with the p.Ala53Thr variant and SNCA triplication confirm co-segregation with PD. Large cohorts have identified SNCA point mutations or multiplications in ~1–2% of familial PD cases, often presenting with levodopa-responsive parkinsonism and cognitive decline (14755720).

Functional Evidence

Mechanistically, the A53T and A30P SNCA mutants accelerate fibrillization and oligomer formation in vitro, with A53T showing the fastest filament assembly (9809558, 10092675). Wild-type alpha-synuclein binds acidic phospholipid membranes and adopts α-helical structure; the A53T mutation enhances filament formation on membranes, whereas A30P impairs membrane binding (10915790). Transgenic mice expressing human A53T SNCA develop progressive motor dysfunction and α-synuclein aggregates, recapitulating PD neuropathology (12084935). These data support a toxic gain-of-function mechanism via accelerated aggregation and disrupted membrane interactions.

Conflicting Evidence

No robust studies have refuted the SNCA–PD link; variability in age of onset and penetrance suggests modifying factors but does not dispute the causal role of SNCA mutations.

Conclusion

SNCA mutations and multiplications cause autosomal dominant PD via accelerated alpha-synuclein aggregation, Lewy body formation, and dopaminergic neuron loss, with definitive genetic and functional evidence. Genetic testing for SNCA variants informs diagnosis, risk assessment, and therapeutic decision-making for PD.

References

  • Nature medicine • 1998 • Accelerated in vitro fibril formation by a mutant alpha-synuclein linked to early-onset Parkinson disease. PMID:9809558
  • The Journal of biological chemistry • 1999 • Both familial Parkinson's disease mutations accelerate alpha-synuclein aggregation. PMID:10092675
  • Experimental neurology • 2004 • Fibrillization of alpha-synuclein and tau in familial Parkinson's disease caused by the A53T alpha-synuclein mutation. PMID:15144854
  • The Journal of biological chemistry • 2000 • alpha-Synuclein membrane interactions and lipid specificity. PMID:10915790
  • Annals of neurology • 2004 • Comparison of kindreds with parkinsonism and alpha-synuclein genomic multiplications. PMID:14755720

Evidence Based Scoring (AI generated)

Gene–Disease Association

Definitive

Multiple unrelated kindreds, autosomal dominant segregation, missense variants and multiplications, concordant pathology and function

Genetic Evidence

Strong

Missense mutations and multiplications in ≥19 probands; co-segregation in multiple families

Functional Evidence

Strong

Mutants accelerate aggregation, disrupt membrane binding, and cause PD-like pathology in models