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PRR12 – Neuroocular Syndrome

Limited clinical evidence supports an association between PRR12 and neuroocular syndrome. A single 11-year-old patient harbored a novel de novo frameshift variant c.1549_1568del (p.Pro517AlafsTer35) consistent with haploinsufficiency and presented with intellectual disability (HP:0001249), short stature (HP:0004322), mild scoliosis, and attention deficit hyperactivity disorder (HP:0007018) (PMID:38798311). No additional familial segregation or recurrent variants have yet been reported.

Functional characterization is limited to expression and localization studies demonstrating nuclear PRR12 expression in neural tissues, without patient-derived cellular or animal models to confirm pathogenic mechanisms. Additional reports and functional assays are needed to establish definitive disease causality. Identification of PRR12 variants should be considered in diagnostic gene panels for early-onset neurodevelopmental and ocular syndromes.

References

  • Frontiers in pediatrics • 2024 • Case Report: Identification of a novel PRR12 variant in a Chinese boy with developmental delay and short stature. PMID:38798311

Evidence Based Scoring (AI generated)

Gene–Disease Association

Limited

Single proband with de novo LoF variant consistent with haploinsufficiency ([PMID:38798311]); no segregation or replication

Genetic Evidence

Limited

One LoF variant in a single proband; no additional cases or segregation

Functional Evidence

Limited

Expression/localization studies only; no functional patient models